Annotation Detail

Information
Associated Genes
TREX1
Associated Variants
ATRIP c.*1442G>A, TREX1 p.Arg114His (p.R114H) ( ENST00000433541.1, ENST00000444177.1, ENST00000456089.1, ENST00000492235.2, ENST00000625293.3, ENST00000635452.2, ENST00000320211.10 )
ATRIP c.*1442G>C, TREX1 p.Arg114Pro (p.R114P) ( ENST00000433541.1, ENST00000444177.1, ENST00000456089.1, ENST00000492235.2, ENST00000625293.3, ENST00000635452.2, ENST00000320211.10 )
ATRIP c.*1442G>A, TREX1 p.Arg114His (p.R114H) ( ENST00000433541.1, ENST00000444177.1, ENST00000456089.1, ENST00000492235.2, ENST00000625293.3, ENST00000635452.2, ENST00000320211.10 )
ATRIP c.*1442G>C, TREX1 p.Arg114Pro (p.R114P) ( ENST00000433541.1, ENST00000444177.1, ENST00000456089.1, ENST00000492235.2, ENST00000625293.3, ENST00000635452.2, ENST00000320211.10 )
Associated Disease
Aicardi-Goutieres syndrome 1
Source Database
DisGeNET
Description
The TREX1R114H/R114H homodimer has dysfunctional dsDNA and ssDNA degradation activities and does not detectibly inhibit the TREX1WT enzyme, whereas the TREX1WT/R114H heterodimer has a functional dsDNA degradation activity, supporting the recessive genetics of TREX1 R114H in AGS.
Pubmed
18805785
Original source reporting the Gene Disease association
BeFree
DisGENET score for the Gene Disease association
0.445971721185767
Year of publication
2008
Drugs